Simultaneous bilateral pallidoansotomy for idiopathic dystonia musculorum deformans

  • Robert P. Iacono
  • , Sandra M. Kuniyoshi
  • , Russell R. Lonser
  • , George Maeda
  • , Anthony M. Inae
  • , Stephen Ashwal

Research output: Contribution to journalArticlepeer-review

Abstract

A 17-year-old Russian male with a 9-year diagnosed history of dystonia musculorum deformans manifested as severe tortipelvis, lordosis, and axial and appendicular spastic dystonia, refractory to medical therapy, is reported. This patient underwent a simultaneous bilateral pallidoansotomy with dramatic results. Postoperative evaluation revealed sustained alleviation of all dystonic symptoms and abnormal movements. Rapid recovery of useful strength in all limbs as well as dramatic improvement in coordination occurred. Bilateral posteroventral pallidotomy and pallidoansotomy in the past have proven effective in alleviation of all parkinsonian symptoms, including dyskinesia and dystonia, without the concurrent risk of intransigent side effects associated with bilateral thalamotomy or other stereotactic surgical procedures. Pallidoansotomy may prove to be the treatment of choice for idiopathic torsion dystonia and merits further investigation.

Original languageEnglish
Pages (from-to)145-148
Number of pages4
JournalPediatric Neurology
Volume14
Issue number2
DOIs
StatePublished - Feb 1996

ASJC Scopus Subject Areas

  • Pediatrics, Perinatology, and Child Health
  • Neurology
  • Developmental Neuroscience
  • Clinical Neurology

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